Safety, Tolerability, Pharmacokinetics, and Preliminary Efficacy of PLX-200 in Pediatric Patients (Master Protocol)
2026年7月28日 更新者:Polaryx Therapeutics, Inc.
An Open-Label, Multicenter, Phase 2 Study to Evaluate Safety, Tolerability, Pharmacokinetics, and Preliminary Efficacy of PLX-200 in Pediatric Patients With Lysosomal Storage Disorders (SOTERIA)
The purpose of this study is to evaluate the safety, tolerability and clinical activity of PLX-200 in pediatric patients with lysosomal storage disorders.
調査の概要
詳細な説明
This is an open-label, proof-of-concept, Phase 2 basket trial evaluating the safety, tolerability, and clinical activity of PLX-200 in pediatric participants with lysosomal storage disorders (LSDs) including CLN2, CLN3, Sandhoff disease, and Krabbe disease.
Participants will receive PLX-200 oral solution twice daily (BID) for approximately 101 weeks, comprising of a 5-week Titration Period and 96-week Maintenance Period.
Clinical activity will be evaluated using synthetic control comparisons.
Dosing strategies and study durations for all other indications will be defined in their respective ISAs.
研究の種類
介入
入学 (推定)
24
段階
- フェーズ2
連絡先と場所
このセクションには、調査を実施する担当者の連絡先の詳細と、この調査が実施されている場所に関する情報が記載されています。
研究連絡先
- 名前:Minsu Kang, PhD
- 電話番号:217-779-7736
- メール:minsukang@polaryx.com
参加基準
研究者は、適格基準と呼ばれる特定の説明に適合する人を探します。これらの基準のいくつかの例は、人の一般的な健康状態または以前の治療です。
適格基準
就学可能な年齢
- 子
健康ボランティアの受け入れ
いいえ
説明
Inclusion Criteria:
- Male or female participants aged 2 to 15 years at the time of informed consent. Any deviations must be approved in advance by the Medical Monitor and Sponsor.
Genetically confirmed diagnosis of one of the four LSDs included in this study: CLN2, CLN3, Sandhoff disease or Krabbe disease. Diagnosis must be supported by all of the following:
- Age of symptom onset consistent with the targeted subtype,
- Relevant clinical manifestations, and
- Documented genotype at Screening or prior to enrollment. If no genotype is available at Screening, blood samples will be collected for genetic analysis as part of study procedures.
- Written informed consent must be obtained from the participant's parent(s) or legal guardian(s). Assent must also be obtained from the participant, when applicable, in accordance with local regulations and the participant's developmental status.
- Parent(s) or legal guardian(s) must demonstrate willingness and ability to comply with the protocol, including adherence to all required baseline, treatment, and follow-up assessments.
Exclusion Criteria:
- The participant has a known inherited neurologic disease other than the targeted lysosomal storage disorder subtype.
- The participant has a neurological illness unrelated to the study indication that may independently cause cognitive or motor decline.
- The participant requires ventilatory support, except for noninvasive support during sleep (e.g., Continuous Positive Airway Pressure [CPAP], Bilevel Positive Airway Pressure [BiPAP]).
- The participant has moderate or severe hepatic dysfunction, defined as alanine aminotransferase (ALT), aspartate aminotransferase (AST), or total bilirubin greater than 3 times the upper limit of normal (ULN), except in cases of Gilbert syndrome. The participant has a diagnosis of primary biliary cirrhosis.
- The participant has clinically significant anemia
- The participant has a body surface area (BSA)-adjusted eGFR <90 mL/min/1.73m2 at Screening or baseline.
- The participant has a history or current diagnosis of gallbladder disease (e.g., cholelithiasis or cholecystitis).
- The participant has a known hypersensitivity to gemfibrozil or any component of the study drug.
The participant is currently using, or is expected to require during the study, any of the following medications which are contraindicated with PLX-200:
- HMG-CoA reductase inhibitors
- Repaglinide (Prandin®)
- Dasabuvir (Exviera®)
- Selexipag (Uptravi®)
- Pioglitazone (Actos®)
- Fibrate medication (e.g., gemfibrozil, fenofibrate). Participants must not have received gemfibrozil or other fibrates for at least 2 weeks or five half-lives, whichever is shorter, before Visit 2 (Day 1). They may not receive gemfibrozil or other fibrates during the study
- Participants receiving Zavesca® (miglustat) or any other prohibited therapies must be willing to discontinue these therapies, complete a washout period (2 weeks or five half-lives, whichever is shorter) prior to Visit 2 (Day 1), and refrain from receiving them while they are participating in the study. If participants were previously on Brineura®, they must complete a 3-month washout period prior to Visit 2 (Day 1) and refrain from receiving it while they are participating in the study.
- The participant has a medical condition or personal circumstance that, in the opinion of the Investigator or Sponsor, could compromise safety, protocol compliance, or the interpretability of study data.
- The participant has received any investigational product or medical device within 30 days prior to the baseline visit that could confound study results or pose additional risk. All participants who have previously received stem cell or gene therapy are excluded regardless of timing.
- The participant receives systemic anticoagulant therapy (e.g., warfarin) and is unable or unwilling to comply with increased frequency of INR monitoring during study participation. Note: Participants may be eligible if receiving anticoagulants (e.g., warfarin) provided that INR can be monitored with increased frequency and dose adjustments are implemented to maintain therapeutic range and avoid bleeding complications.
- The participant has uncontrolled seizures, defined as ≥4 generalized tonic-clonic seizures per month or a recent episode of status epilepticus.
- The participant has severe central nervous system abnormalities (e.g., hydrocephalus, intracranial shunt).
- The participant has a history of clinically significant arrhythmia or QTc prolongation at Screening or baseline.
- The participant is pregnant or breastfeeding or is a female showing signs of pubertal development (e.g., Tanner Stage ≥2) who is unable or unwilling to undergo pregnancy testing at Screening or baseline. All such determinations must involve consultation with the Medical Monitor and follow the procedures outlined in each ISA.
研究計画
このセクションでは、研究がどのように設計され、研究が何を測定しているかなど、研究計画の詳細を提供します。
研究はどのように設計されていますか?
デザインの詳細
- 主な目的:処理
- 割り当て:非ランダム化
- 介入モデル:単一グループの割り当て
- マスキング:なし(オープンラベル)
武器と介入
参加者グループ / アーム |
介入・治療 |
|---|---|
|
実験的:PLX-200 (CLN3 Disease Cohort)
An Open-Label, Multicenter, Phase 2 Study to Evaluate Safety, Tolerability, Pharmacokinetics, and Preliminary Efficacy of PLX-200 in Pediatric Patients with CLN3 Disease (Juvenile Neuronal Ceroid Lipofuscinosis) (CLN3 Intervention-Specific Assessment [ISA] Under the PLX-200-600 Master Protocol)
|
PLX-200 will be BID, with equal doses given approximately 12 hours apart, 30 minutes before the morning and evening meals, for 101 weeks (5-week Titration Period and 96-week Maintenance Period) based on each participant's weight.
Dosing will begin with a 5-week TP based on the participant's weight group to achieve a target maintenance dose (TMD).
他の名前:
|
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実験的:PLX-200 (CLN2 Disease Cohort)
An Open-Label, Multicenter, Phase 2 Study to Evaluate Safety, Tolerability, Pharmacokinetics, and Preliminary Efficacy of PLX-200 in Pediatric Patients with CLN2 Disease (Late-Infantile Neuronal Ceroid Lipofuscinosis) (CLN2 Intervention-Specific Assessment [ISA] Under the PLX-200-600 Master Protocol)
|
PLX-200 will be BID, with equal doses given approximately 12 hours apart, 30 minutes before the morning and evening meals, for 101 weeks (5-week Titration Period and 96-week Maintenance Period) based on each participant's weight.
Dosing will begin with a 5-week TP based on the participant's weight group to achieve a target maintenance dose (TMD).
他の名前:
|
|
実験的:PLX-200 (Sandhoff Disease Cohort)
An Open-Label, Multicenter, Phase 2 Study to Evaluate Safety, Tolerability, Pharmacokinetics, and Preliminary Efficacy of PLX-200 in Pediatric Patients with Sandhoff Disease (GM2 Gangliosidosis Type II) (Sandhoff Disease Intervention-Specific Assessment [ISA] Under the PLX-200-600 Master Protocol)
|
PLX-200 will be BID, with equal doses given approximately 12 hours apart, 30 minutes before the morning and evening meals, for 101 weeks (5-week Titration Period and 96-week Maintenance Period) based on each participant's weight.
Dosing will begin with a 5-week TP based on the participant's weight group to achieve a target maintenance dose (TMD).
他の名前:
|
|
実験的:PLX-200 (Krabbe Disease Cohort)
An Open-Label, Multicenter, Phase 2 Study to Evaluate Safety, Tolerability, Pharmacokinetics, and Preliminary Efficacy of PLX-200 in Pediatric Patients with Krabbe Disease (Globoid Cell Leukodystrophy) (Krabbe Disease Intervention-Specific Assessment [ISA] Under the PLX-200-600 Master Protocol)
|
PLX-200 will be BID, with equal doses given approximately 12 hours apart, 30 minutes before the morning and evening meals, for 101 weeks (5-week Titration Period and 96-week Maintenance Period) based on each participant's weight.
Dosing will begin with a 5-week TP based on the participant's weight group to achieve a target maintenance dose (TMD).
他の名前:
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この研究は何を測定していますか?
主要な結果の測定
結果測定 |
メジャーの説明 |
時間枠 |
|---|---|---|
|
To evaluate the safety and tolerability of PLX-200 in study participants 2 to 15 years old1 with LSDs2 during the treatment period.
時間枠:Until 30 days after the last administration of the study drug.
|
Incidence and severity of treatment-emergent adverse events (TEAEs) until 30 days after the last administration of the study drug as well as withdrawals due to the TEAEs.
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Until 30 days after the last administration of the study drug.
|
|
To evaluate the safety and tolerability of PLX-200 in study participants 2 to 15 years old1 with LSDs2 during the treatment period.
時間枠:30 days after the last administration of the study drug
|
Incidence and severity of serious adverse events (SAEs) until 30 days after the last administration of the study drug.
|
30 days after the last administration of the study drug
|
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To evaluate the change from baseline in clinical laboratory parameters in study participants 2 to 15 years old with LSDs during the treatment period.
時間枠:Week 102
|
Week 102
|
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To evaluate the change from baseline in physical examination results in study participants 2 to 15 years old with LSDs during the treatment period.
時間枠:Week 102
|
Week 102
|
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To evaluate the change from baseline vital signs in study participants 2 to 15 years old with LSDs during the treatment period.
時間枠:Week 102
|
Week 102
|
|
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To evaluate the change from baseline in 12-lead electrocardiogram in study participants 2 to 15 years old with LSDs during the treatment period.
時間枠:Week 102
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Week 102
|
二次結果の測定
結果測定 |
メジャーの説明 |
時間枠 |
|---|---|---|
|
To evaluate the clinical activity of PLX-200 in study participants 2 to 15 years old with LSDs as measured by each respective instrument as specified in the Intervention Specific Assessment (ISA).
時間枠:Week 102
|
Week 102
|
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Change from Baseline in Vineland Adaptive Behavior Scales, Third Edition (VABS-3) Score
時間枠:Week 102
|
To evaluate the clinical activity of PLX-200 in pediatric patients with late-infantile Krabbe/Sandhoff/CLN2/CLN3 disease using the Vineland Adaptive Behavior Scales, Third Edition (VABS-3), over 101 weeks of treatment.
|
Week 102
|
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Caregiver Global Impression of Severity
時間枠:Week 102
|
To evaluate clinical activity of PLX-200 as reported by the caregiver.
Change from baseline to Week 102 in Caregiver Global Impression of Severity (CaGI-S).
|
Week 102
|
協力者と研究者
ここでは、この調査に関係する人々や組織を見つけることができます。
研究記録日
これらの日付は、ClinicalTrials.gov への研究記録と要約結果の提出の進捗状況を追跡します。研究記録と報告された結果は、国立医学図書館 (NLM) によって審査され、公開 Web サイトに掲載される前に、特定の品質管理基準を満たしていることが確認されます。
主要日程の研究
研究開始 (推定)
2026年12月1日
一次修了 (推定)
2028年12月31日
研究の完了 (推定)
2029年2月1日
試験登録日
最初に提出
2026年7月17日
QC基準を満たした最初の提出物
2026年7月28日
最初の投稿 (実際)
2026年7月31日
学習記録の更新
投稿された最後の更新 (実際)
2026年7月31日
QC基準を満たした最後の更新が送信されました
2026年7月28日
最終確認日
2026年7月1日
詳しくは
本研究に関する用語
追加の関連 MeSH 用語
- 脳疾患
- 中枢神経系疾患
- 神経系疾患
- 代謝、先天性エラー
- 遺伝性疾患、先天性疾患
- 代謝疾患
- 脱髄疾患
- 脂質代謝異常症
- 脳疾患、代謝、先天性
- 脳疾患、代謝
- 遺伝性中枢神経系脱髄疾患
- 白質脳症
- 脂質代謝、先天性エラー
- リソソーム蓄積症、神経系
- スフィンゴリピドーシス
- リピドーシス
- ガングリオシドーシス、GM2
- ガングリオシドーシス
- 先天性、遺伝性、および新生児の疾患と異常
- 栄養および代謝疾患
- リソソーム蓄積症
- 白質ジストロフィー、球状細胞
- サンドホフ病
- 有機化学物質
- エーテル
- 脂肪酸
- 脂質
- 炭化水素
- 炭化水素、周期的
- 酸、非環式
- カルボン酸
- 炭化水素、芳香
- フェノール
- ベンゼン誘導体
- ペンタン酸
- バラレート
- 脂肪酸、揮発性
- 酪酸
- フェニルエーテル
- フィブリック酸
- 等菌
- Gemfibrozil
その他の研究ID番号
- PLX-200-600
個々の参加者データ (IPD) の計画
個々の参加者データ (IPD) を共有する予定はありますか?
いいえ
医薬品およびデバイス情報、研究文書
米国FDA規制医薬品の研究
はい
米国FDA規制機器製品の研究
いいえ
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