- ICH GCP
- US Clinical Trials Registry
- Klinisk forsøg NCT07571525
Thymic Disease, Autoimmunity, and Neuromuscular Junction Integrity in Myasthenia Gravis (TAILOR-MG)
Thymic Disease, Autoimmunity, and Neuromuscular Junction Integrity in Myasthenia Gravis: An Observational Prospective Translational Cohort Study
The goal of this observational study is to investigate the clinical, immunological, and neuromuscular features associated with the development and progression of myasthenia gravis (MG) in adult patients with thymic abnormalities and/or MG-related antibodies, including individuals with or without clinically manifest disease.
The main questions it aims to answer are:
- Whether integrated clinical, serological, and histopathological profiles are associated with the presence of MG and can predict disease onset or progression
- Wheter systemic immune markers are associated with disease activity, progression, and neuromuscular junction alterations
Participants will:
- Undergo clinical, neurological, and neurophysiological assessments at baseline and during follow-up
- Provide blood samples for serological and immunological analyses
- Provide thymic tissue and residual intercostal muscle samples (when undergoing clinically indicated thymectomy) for research analyses
- Attend follow-up visits at 6, 12, and 18 months
- Record daily symptoms using an electronic patient-reported outcome tool (for participants with MG)
Studieoversigt
Status
Detaljeret beskrivelse
Myasthenia gravis (MG) is an autoimmune disorder of the neuromuscular junction characterized by fluctuating muscle weakness and fatigability. In most cases, the disease is associated with antibodies directed against the acetylcholine receptor (AChR) and is frequently linked to thymic abnormalities, including thymoma and thymic hyperplasia. Despite the recognized role of the thymus in MG pathogenesis, the mechanisms driving the transition from thymic autoimmunity to clinically manifest disease remain incompletely understood, and reliable biomarkers for disease prediction and monitoring are lacking.
This study is a single-center, prospective, observational translational cohort designed to comprehensively characterize the clinical, neurophysiological, serological, immunological, and histopathological features of patients with thymic abnormalities and/or MG. The study adopts a multimodal approach integrating routine clinical assessments with advanced laboratory and tissue-based analyses, with the aim of identifying biological mechanisms and potential biomarkers associated with MG onset and progression.
A total of 40 adult participants will be enrolled and stratified into four predefined groups:
- patients with thymoma and MG-related antibodies,
- patients with other thymic abnormalities and MG-related antibodies,
- thymoma patients without MG-related antibodies (control group), and
- patients with established MG without thymic abnormalities. This design enables comparison across different clinical and immunological phenotypes and supports exploratory evaluation of circulating and tissue-based biomarkers.
At baseline, all participants will undergo standardized clinical and neurological evaluation, including validated MG-specific outcome measures, neurophysiological testing (repetitive nerve stimulation and single-fiber electromyography), and blood sampling for serological and immunological analyses. Imaging assessments, including chest CT for thymic characterization and orbital MRI for evaluation of extraocular muscle involvement, will be performed according to clinical indications. Participants will be followed longitudinally for 18 months, with scheduled evaluations at 6, 12, and 18 months. Follow-up assessments will include repeated clinical, neurophysiological, and serological measurements to capture disease evolution over time and to evaluate the relationship between biological markers and clinical outcomes.
In participants undergoing thymectomy as part of standard clinical care, thymic tissue will be collected for routine diagnostic purposes, with additional samples used for research analyses. Residual intercostal muscle tissue obtained within the surgical field will also be collected, without modification of the surgical procedure or additional risk to the patient. These samples will be used to investigate structural and molecular features of the neuromuscular junction, including receptor organization and evidence of immune-mediated damage.
Peripheral blood samples collected at baseline and follow-up visits will be used to characterize systemic immune profiles, including autoantibodies, cytokines, and complement activation products. These data will be integrated with clinical, neurophysiological, and histopathological findings to explore associations with MG onset, severity, and progression.
In participants with established MG, longitudinal symptom monitoring will be performed using an electronic patient-reported outcome tool based on questionnaires routinely used in clinical practice. Patients will record daily symptoms across key domains (ocular, bulbar, respiratory, and limb involvement), enabling high-resolution assessment of symptom fluctuations over time. These data will be compared with clinical outcome measures collected during scheduled visits to evaluate concordance and the potential added value of continuous symptom monitoring.
Overall, this study aims to provide an integrated characterization of MG across clinical, biological, and tissue levels, with the ultimate goal of identifying early predictors of disease development and progression, improving risk stratification, and supporting future strategies for personalized monitoring and intervention.
Undersøgelsestype
Tilmelding (Anslået)
Kontakter og lokationer
Studiekontakt
- Navn: Stefano C Previtali
- Telefonnummer: 0039 0226433036
- E-mail: neuromuscolare@hsr.it
Undersøgelse Kontakt Backup
- Navn: Benedetta Sorrenti
- Telefonnummer: 0039 0226433036
- E-mail: neuromuscolare@hsr.it
Studiesteder
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Milan, Italien, 20132
- IRCCS Ospedale San Raffaele
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Kontakt:
- Stefano C Previtali
- Telefonnummer: 0039 0226433036
- E-mail: neuromuscolare@hsr.it
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Kontakt:
- Benedetta Sorrenti
- Telefonnummer: 0226433036
- E-mail: neuromuscolare@hsr.it
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Deltagelseskriterier
Berettigelseskriterier
Aldre berettiget til at studere
- Voksen
- Ældre voksen
Tager imod sunde frivillige
Prøveudtagningsmetode
Studiebefolkning
The study population consists of adult patients (≥18 years) undergoing evaluation for thymic abnormalities and/or myasthenia gravis at a tertiary referral center. Participants include individuals with thymoma or other thymic pathology, with or without MG-related antibodies and with or without clinically manifest myasthenia gravis, as well as patients with established myasthenia gravis without evidence of thymic abnormalities.
Participants are recruited from routine clinical care settings, including neurology and thoracic surgery units, and reflect a spectrum of clinical and immunological phenotypes relevant to disease development and progression. This population enables the investigation of the relationship between thymic pathology, systemic immune profiles, and neuromuscular junction involvement in myasthenia gravis.
Beskrivelse
Inclusion Criteria:
- Age ≥18 years at the time of informed consent
- Ability to provide written informed consent and comply with study procedures
- Availability of a serum sample for testing MG-related antibodies
- Availability of chest imaging (CT and/or MRI) to classify thymic status
Participants must also meet the criteria for at least one of the following study groups:
Cohort 1: Thymoma with MG-related antibodies
- Histologically or radiologically confirmed thymoma
- Presence of at least one pathogenic MG-related antibody (AChR)
- Presence or absence of clinically manifest myasthenia gravis
Cohort 2: Other thymic abnormalities with MG-related antibodies
- Imaging or histological evidence of non-thymomatous thymic pathology (e.g., thymic hyperplasia)
- Presence of at least one pathogenic MG-related antibody (AChR)
- Presence or absence of clinically manifest myasthenia gravis
Cohort 3: Thymoma without MG-related antibodies
- Histologically or radiologically confirmed thymoma
- Negative for pathogenic MG-related antibodies (AChR)
- No clinical diagnosis or symptoms suggestive of myasthenia gravis
Cohort 4: Myasthenia gravis without thymic abnormalities
Established clinical diagnosis of myasthenia gravis with consistent clinical features, supported by at least one of the following:
- Seropositivity for MG-related antibodies (AChR, MuSK, or LRP4), or
- Abnormal neuromuscular transmission demonstrated by SFEMG or RNS, or
- Improvement of MG signs with treatment such as oral acetylcholinesterase inhibitors, plasma exchange, IVIg, or corticosteroids
- Absence of thymic abnormalities on CT or MRI
Exclusion Criteria:
- Inability to provide informed consent
- Other neuromuscular diseases that could interfere with interpretation of clinical or neurophysiological findings
- Severe uncontrolled systemic illness that, in the investigator's judgment, may limit participation or confound study outcomes
- Any medical or psychiatric condition, or history of substance abuse, that may compromise adherence to study procedures
- Pregnancy or breastfeeding
Studieplan
Hvordan er undersøgelsen tilrettelagt?
Design detaljer
Kohorter og interventioner
Gruppe / kohorte |
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Patients with thymoma and MG-related antibodies
Patients with histologically or radiologically confirmed thymoma and presence of MG-related antibodies (AChR), with or without clinically manifest myasthenia gravis.
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Patients with other thymic abnormalities and MG-related antibodies
Patients with non-thymomatous thymic pathology (e.g., thymic hyperplasia) and presence of MG-related antibodies (AChR), with or without clinically manifest myasthenia gravis.
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Thymoma patients without MG-related antibodies
Patients with confirmed thymoma, negative for MG-related antibodies, and without clinical signs or diagnosis of myasthenia gravis.
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Patients with established MG without thymic abnormalities
Patients with an established diagnosis of myasthenia gravis based on clinical, serological, and/or neurophysiological criteria, and no evidence of thymic abnormalities.
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Hvad måler undersøgelsen?
Primære resultatmål
Resultatmål |
Foranstaltningsbeskrivelse |
Tidsramme |
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Qualitative assessment of neuromuscular junction structural abnormalities in intercostal muscle samples
Tidsramme: At the time of thymectomy (baseline)
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The primary outcome is the qualitative assessment of neuromuscular junction structural abnormalities in residual intercostal muscle samples collected from participants undergoing clinically indicated thymectomy.
Neuromuscular junction integrity will be evaluated using histological, immunofluorescence, and ultrastructural analyses, including assessment of acetylcholine receptor clustering, IgG and complement deposition, postsynaptic fold morphology, and features of synaptic remodeling or immune-mediated injury.
Structural abnormalities will be described in terms of presence or absence and, where applicable, semi-quantitative grading.
Findings will be compared across participant groups according to thymic pathology, MG-related antibody status, and the presence or absence of clinically manifest myasthenia gravis.
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At the time of thymectomy (baseline)
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Sekundære resultatmål
Resultatmål |
Foranstaltningsbeskrivelse |
Tidsramme |
|---|---|---|
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Qualitative assessment of thymic histopathological features
Tidsramme: At the time of thymectomy (baseline)
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Qualitative assessment of thymic histopathological features in thymic tissue collected from participants undergoing clinically indicated thymectomy.
Thymic tissue will be evaluated for histopathological features including thymoma subtype, thymic hyperplasia, germinal centers, lymphoid infiltrates, and AIRE expression, where applicable.
Histopathological findings will be described in terms of presence or absence and, where applicable, semi-quantitative grading.
These features will be analyzed in relation to neuromuscular junction structural abnormalities identified in intercostal muscle samples, as well as according to MG-related antibody status and the presence or absence of clinically manifest myasthenia gravis.
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At the time of thymectomy (baseline)
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Change in Myasthenia Gravis Activities of Daily Living (MG-ADL) score
Tidsramme: Baseline, 6, 12, and 18 months
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The MG-ADL is an 8-item scale assessing myasthenia gravis-related symptoms and functional impairment, with a total score ranging from 0 to 24.
Higher scores indicate greater disease burden.
Changes from baseline will be evaluated during follow-up and analyzed in relation to biological markers, neuromuscular junction findings, and electronically collected patient-reported symptom scores.
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Baseline, 6, 12, and 18 months
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Change in Quantitative Myasthenia Gravis (QMG) score
Tidsramme: Baseline, 6, 12, and 18 months
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The QMG is a 13-item examiner-administered scale assessing muscle weakness and fatigability, with a total score ranging from 0 to 39. Higher scores indicate greater disease severity.
Changes from baseline will be evaluated during follow-up and analyzed in relation to biological markers, neuromuscular junction findings, and electronically collected patient-reported symptom scores.
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Baseline, 6, 12, and 18 months
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Change in serum MG-related autoantibody levels over time
Tidsramme: Baseline, 6, 12, and 18 months
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Measurement of serum levels of MG-related autoantibodies, including acetylcholine receptor (AChR) antibodies, assessed using cell-based assays and ELISA assays.
Autoantibody levels will be reported as titers and evaluated at baseline and during follow-up to describe their distribution and longitudinal changes.
These measurements will be analyzed in relation to clinical and neurophysiological findings, as well as thymyc histopathology and neuromuscular junction structural features.
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Baseline, 6, 12, and 18 months
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Change in plasma and serum levels of complement activation products
Tidsramme: Baseline, 6, 12, and 18 months
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The secondary outcome is the change in plasma and serum levels of complement activation products, including C3b, C5a, and sC5b-9, assessed using immunoassay-based methods.
Changes in complement activation product levels will be evaluated from baseline to follow-up visits and reported as concentrations.
These measurements will be analyzed in relation to clinical and neurophysiological findings, as well as thymic histopathology and neuromuscular junction structural features.
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Baseline, 6, 12, and 18 months
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Change in mean daily composite MG symptom questionnaire score (electronically collected)
Tidsramme: Baseline and up to 18 months
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The electronic tool consists of a structured daily questionnaire in which patients report symptom severity across four domains (ocular, bulbar, respiratory, and limb involvement), using a visual analogue scale (VAS, 0-10 for each item; 0 = no symptoms, 10 = maximum severity).
Individual item scores are summed to generate a daily composite score (range 0-40), with higher scores indicating greater symptom burden.
The mean daily composite score will be calculated over predefined time intervals during follow-up, and changes from baseline will be evaluated longitudinally.
The questionnaire is based on domains derived from the Myasthenia Gravis Activities of Daily Living (MG-ADL) instrument.
Patient-reported scores will be compared with MG-ADL and Quantitative Myasthenia Gravis (QMG) scores assessed at scheduled visits to evaluate concordance and the ability to capture symptom fluctuations over time.
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Baseline and up to 18 months
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Samarbejdspartnere og efterforskere
Sponsor
Efterforskere
- Ledende efterforsker: Stefano C Previtali, IRCCS Ospedale San Raffaele
Datoer for undersøgelser
Studer store datoer
Studiestart (Anslået)
Primær færdiggørelse (Anslået)
Studieafslutning (Anslået)
Datoer for studieregistrering
Først indsendt
Først indsendt, der opfyldte QC-kriterier
Først opslået (Faktiske)
Opdateringer af undersøgelsesjournaler
Sidste opdatering sendt (Faktiske)
Sidste opdatering indsendt, der opfyldte kvalitetskontrolkriterier
Sidst verificeret
Mere information
Begreber relateret til denne undersøgelse
Nøgleord
Yderligere relevante MeSH-vilkår
- Sygdomme i nervesystemet
- Neoplasmer efter sted
- Neoplasmer
- Neuromuskulære sygdomme
- Autoimmune sygdomme
- Sygdomme i immunsystemet
- Neoplasmer efter histologisk type
- Autoimmune sygdomme i nervesystemet
- Neurodegenerative sygdomme
- Thoracale neoplasmer
- Lymfesygdomme
- Paraneoplastiske syndromer, nervesystemet
- Neoplasmer i nervesystemet
- Paraneoplastiske syndromer
- Neuromuskulære Junction-sygdomme
- Neoplasmer, komplekse og blandede
- Thymus neoplasmer
- Hemiske og lymfatiske sygdomme
- Myasthenia gravis
- Thymom
Andre undersøgelses-id-numre
- OSRSCP_TAILOR-MG
Plan for individuelle deltagerdata (IPD)
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